This paper reported a case of bilateral occipital lobe infarction combined with Anton syndrome after traumatic cerebral herniation. The patient did not receive early postoperative visual function examinations due to no complaint of visual dysfunction. Three weeks after operation, fixed eyeballs and upward gaze were found during physical examination, and bilateral occipital lobe infarction was revealed by CT and MRI. The patient was then managed with dehydration, neurotrophy and hyperbaric oxygen treatment, while the effect was limited. On basis of literature review, some issues related to this case were discussed.